Mandibular fibrous dysplasia complicated with aneurysmal bone cyst: a case report

doi:10.19438/j.cjoms.2025.01.017

Abstract

Abstract: Fibrous dysplasia is a congenital non-hereditary disorder of bone dysplasia in which fibrous tissue replaces normal bone tissue. Aneurysmal bone cysts are lytic lesions made up of multiple blood-filled cavities. It is rare for two diseases to occur in the same body at the same time, and it is even rarer for the disease to occur in the same area. This article reported a case of jaw complicated by poor fibrous structure and aneurysmal bone cyst, and reviewed the relevant literature for discussion.

Key words: Fibrous dysplasia, Aneurysmal bone cyst, Jaw

CLC Number:

R739.8

ZHANG Tao, DUAN Xiao-feng. Mandibular fibrous dysplasia complicated with aneurysmal bone cyst: a case report[J]. China Journal of Oral and Maxillofacial Surgery, 2025, 23(1): 98-100.

References

[1] Tafti D, Cecava ND.Fibrous dysplasia[M]. StatPearls. Treasure Island (FL): StatPearls Publishing LLC, 2024.
[2] Stevens KJ, Stevens JA.Aneurysmal bone cysts[M]. StatPearls. Treasure Island (FL): StatPearls Publishing LLC, 2024.
[3] Menon S, Venkatswamy S, Ramu V, et al.Craniofacial fibrous dysplasia: surgery and literature review[J]. Ann Maxillofac Surg, 2013, 3(1): 66-71.
[4] Kim DY.Current concepts of craniofacial fibrous dysplasia: pathophysiology and treatment[J]. Arch Craniofac Surg, 2023, 24(2): 41-51.
[5] Szymczuk V, Taylor J, Boyce AM.Craniofacial fibrous dysplasia: clinical and therapeutic implications[J]. Curr Osteoporos Rep, 2023, 21(2): 147-153.
[6] Özcan Í, Ünsal G, Koca RB, et al.Craniofacial fibrous dysplasia involvements of mccune-albright syndrome: a review with an additional case[J]. Curr Med Imaging, 2021, 17(7): 864-870.
[7] Szymczuk V, Florenzano P, de Castro LF, et al. Fibrous dysplasia/McCune-Albright syndrome[C]//Adam MP, Feldman J, Mirzaa GM, et al. GeneReviews[M]. Seattle(WA): University of Washington, Seattle, 1993.
[8] Obermeier KT, Hartung JT, Hildebrandt T, et al.Fibrous dysplasia of the jaw: advances in imaging and treatment[J]. J Clin Med, 2023, 12(12): 4100.
[9] 韩志巍, 文娣娣, 张劲松, 等. 实性动脉瘤样骨囊肿的影像学表现[J]. 中国医学影像学杂志, 2023, 31(4): 395-399.
Han ZW, Wen DD, Zhang JS, et al.Imaging findings of solid variant of aneurysmal bone cyst[J]. Chinese Journal of Medical Imaging, 2023, 31(4): 395-399.
[10] Li L, Bui MM, Zhang M, et al.Validation of fluorescence in situ hybridization testing of USP6 gene rearrangement for diagnosis of primary aneurysmal bone cyst[J]. Ann Clin Lab Sci, 2019, 49(5): 590-597.
[11] 方奋, 黄宝泉, 陈衍霖. 动脉瘤样骨囊肿的影像诊断[J]. 影像研究与医学应用, 2021, 5(22): 219-220.
Fang F, Huang BQ, Chen YL.Imaging diagnosis of aneurysmal bone cyst[J]. Journal of Imaging Research and Medical Applications, 2021, 5(22): 219-220.
[12] Restrepo R, Zahrah D, Pelaez L, et al.Update on aneurysmal bone cyst: pathophysiology, histology, imaging and treatment[J]. Pediatr Radiol, 2022, 52(9): 1601-1614.
[13] Liu Y, Zhou J, Shi J.Clinicopathology and recurrence analysis of 44 jaw aneurysmal bone cyst cases: a literature review[J]. Front Surg, 2021,8: 678696.
[14] 王敏, 邱连丽, 夏卓漫, 等. 额骨纤维结构不良合并动脉瘤样骨囊肿1例[J]. 医学影像学杂志, 2023, 33(9): 1733-1734.
Wang M, Qiu LL, Xia ZM, et al.Fibrous dysplasia complicated with aneurysmal bone cyst of the frontal bone: one case report[J]. Journal of Medical Imaging, 2023, 33(9): 1733-1734.
[15] Dalle Carbonare M, Manisali M.Surgical management of syndromic versus non-syndromic craniofacial fibrous dysplasia: a systematic review and meta-analysis[J]. Br J Oral Maxillofac Surg, 2022, 60(9): 1166-1175.
[16] Nasri E, Reith JD.Aneurysmal bone cyst: a review[J]. J Pathol Transl Med, 2023, 57(2): 81-87.
[17] Chen YR, Noordhoff MS.Treatment of craniomaxillofacial fibrous dysplasia: how early and how extensive?[J]. Plast Reconstr Surg, 1991, 87(4): 799-800.
[18] Pacino GA, Cocuzza S, Tonoli G, et al.Jawbone fibrous dysplasia: retrospective evaluation in a cases series surgically treated and short review of the literature[J]. Acta Biomed, 2020, 92(1): e2021018.
[19] Valentini V, Cassoni A, Terenzi V, et al.Our experience in the surgical management of craniofacial fibrous dysplasia: what has changed in the last 10 years?[J]. Acta Otorhinolaryngol Ital, 2017, 37(5): 436-443.